Osilodrostat
Indications
Osilodrostat is used for:
Cushing Disease
Adult Dose
Cushing Disease
Indicated for Cushing disease in adults for whom pituitary surgery is not an option or has not been curative
Initial: 2 mg PO BID
Titration
Initially, titrate by 1-2 mg BID, no more frequently than q2weeks based on rate of cortisol changes, individual tolerability, and improvement in Cushing disease signs and symptoms
If patient tolerates 10 mg PO BID and continues to have elevated 24-hr urine free cortisol (UFC) levels >ULN, titrate dosage further by 5 mg BID q2week
Monitor cortisol levels from at least two 24-hour UFC collections q1-2weeks until adequate clinical response maintained
Maintenance
Individualize maintenance dose according to cortisol levels and signs/symptoms
Maintenance dosage varied from 2-7 mg BID in clinical trials
Maximum recommended maintenance dose: 30 mg BID
Once the maintenance dose achieved, monitor cortisol levels at least every 1-2 months or as indicated
Hepatic impairment
Mild (Child-Pugh A): No dose adjustment required
Moderate (Child-Pugh B): Reduce recommended initial dose to 1 mg BID
Severe (Child-Pugh C): Reduce recommended initial dose to 1 mg qHS
More frequent adrenal function monitoring may be required during dose titration in all patients with hepatic impairment
Child Dose
Renal Dose
Renal impairment
No dose adjustment required
Caution in interpreting UFC levels with moderate-to-severe renal impairment, owing to reduced UFC excretion
Administration
May take with or without food
Contra Indications
Precautions
Hypocortisolism
Osilodrostat lowers cortisol levels and can lead to hypocortisolism and sometimes life-threatening adrenal insufficiency
Lowering of cortisol can cause nausea, vomiting, fatigue, abdominal pain, loss of appetite, dizziness; significant lowering may result in hypotension, abnormal electrolyte levels, and hypoglycemia
Can occur at any time during treatment; evaluate for precipitating causes of hypocortisolism (eg, infection, physical stress)
Monitor 24-hr urine free cortisol (UFC), serum or plasma cortisol, and signs/symptoms
QTc prolongation
Associated with dose-dependent QT interval prolongation (maximum mean estimated QTcF increase of up to 5.3 ms at 30 mg), which may cause cardiac arrhythmias
Obtain baseline ECG with QTc interval measurement before initiating and monitor QTc interval thereafter
Correct hypokalemia and/or hypomagnesemia before initiating and monitor periodically during treatment; correct electrolyte abnormalities if indicated
Consider temporary discontinuation if QTc interval >480 ms
Elevated adrenal hormone precursors and androgens
Osilodrostat blocks cortisol synthesis and may increase circulating levels of cortisol and aldosterone precursors (11-deoxy cortisol and 11-deoxycorticosterone) and androgens
Elevated 11-deoxycorticosterone levels may activate mineralocorticoid receptors and cause hypokalemia, edema, and hypertension
Correct hypokalemia before initiating
Pregnancy-Lactation
Pregnancy
Data are not available regarding use in pregnant women to evaluate for a drug-associated risk of major birth defects, miscarriage, or adverse maternal or fetal outcomes
There are risks to the mother and fetus associated with active Cushing syndrome during pregnancy
Clinical considerations
Active Cushing syndrome during pregnancy associated with increased risk of maternal and fetal morbidity and mortality (including gestational diabetes, gestational hypertension, preeclampsia, maternal death, miscarriage, fetal loss, preterm birth)
Animal data
No adverse developmental outcomes observed in reproduction studies in pregnant rats and rabbits when exposed during organogenesis at doses that produced maternal exposures of 7 and 0.5 times the 30-mg BID maximum clinical dose, by AUC
In rabbits, exposures associated with maternal toxicity at 7 times the maximum clinical dose resulted in decreased fetal viability
No adverse developmental outcomes were observed in a prenatal and postnatal development study with administration to pregnant rats from organogenesis through lactation at 8 times the 30-mg BID maximum clinical dose
Lactation
Data are not available regarding presence in human or animal milk, effects on breastfed infants, or effects on milk production
Because of potential for serious adverse effects (eg, adrenal insufficiency), do not breastfeed during treatment and for at least 1 week after discontinuing drug
Interactions
Side Effects
Side effects of Osilodrostat :
>10%
Adrenal insufficiency (43.1%)
Fatigue (38.7%)
Nausea (37.2%)
Headache (30.7%)
Edema (21.2%)
Nasopharyngitis (19.7%)
Vomiting (19%)
Arthralgia (17.5%)
Back pain (15.3%)
Rash (15.3%)
Diarrhea (14.6%)
Blood corticotrophin increased (13.9%)
Dizziness (13.9%)
Abdominal pain (13.1%)
Hypokalemia (12.4%)
Myalgia (12.4%)
Decreased appetite (11.7%)
Hormone level abnormal (11.7%)
Hypotension (11.7%)
Urinary tract infection (11.7%)
Blood testosterone increased (10.9%)
Pyrexia (10.9%)
Anemia (10.2%)
Cough (10.2%)
Hypertension (10.2%)
Influenza (10.2%)
1-10%
Hirsutism (9.5%)
Acne (8.8%)
Dyspepsia (8%)
Insomnia (8%)
Anxiety (7.3%)
Depression (7.3%)
Gastroenteritis (7.3%)
Malaise (6.6%)
Tachycardia (6.6%)
Alopecia (5.8%)
Transaminases increased (4.4%)
ECG QT prolongation (3.6%)
Syncope (1.5%)
Mode of Action
Orally administered steroidogenesis inhibitor of 11-beta-hydroxylase, an enzyme that catalyzes the final step of cortisol synthesis in the adrenal cortex